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J Pediatr Infect Dis 2019; 14(04): 209-212
DOI: 10.1055/s-0037-1608888
Case Report
Georg Thieme Verlag KG Stuttgart · New York

Periocular Cutaneous Mucormycosis Caused by Saksenaea erythrospora

Bunyada Putthirangsiwong
1   Department of Ophthalmology, Ramathibodi Hospital, Mahidol University, Bangkok, Thailand
,
Pornchai Mahaisavariya
1   Department of Ophthalmology, Ramathibodi Hospital, Mahidol University, Bangkok, Thailand
,
Weerawan Chokthaweesak
1   Department of Ophthalmology, Ramathibodi Hospital, Mahidol University, Bangkok, Thailand
,
Dinesh Selva
2   Department of Ophthalmology & Visual Sciences, University of Adelaide and South Australian Institute of Ophthalmology, Adelaide, Australia
› Author Affiliations
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Publication History

04 July 2017

18 October 2017

Publication Date:
06 December 2017 (online)

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Abstract

Saksenaea erythrospora is a rare pathogen in humans. Ten adult cases have been previously reported, eight manifested with cutaneous infection, and two presented with invasive rhinosinusitis infection. The authors present a 16-month-old boy with progressive painful mass at the right medial canthus and upper cheek that was unresponsive to broad-spectrum antibiotics. He underwent an anterior orbitotomy and biopsy. Histopathology revealed broad nonseptate sterile hyphae and grew S. erythrospora, which was confirmed by molecular techniques. The patient was treated with intravenous liposomal amphotericin B and oral itraconazole combined with aggressive surgical debridement. The patient made a complete recovery without long-term complications at 4 months of follow-up. Primary cutaneous mucormycosis caused by S. erythrospora may rarely involve the periocular region and mimic chronic dacryocystitis. We report the first case of pediatric periocular cutaneous mucormycosis caused by S. erythrospora.

Keywords

cutaneous mucormycosis - dacryocystis - Saksenaea erythrospora - liposomal amphotericin B