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CC BY-NC-ND 4.0 · Arquivos Brasileiros de Neurocirurgia: Brazilian Neurosurgery
DOI: 10.1055/s-0043-1776277
Case Report

Delayed Posttraumatic Blepharocele: A Rare Case Report with Review of the Literature

Blefarocele pós-traumática tardia: relato de caso raro com revisão da literatura
Amey P. Patankar 
1   Department of Neurosurgery, Baroda Medical College and SSG Hospital, Vadodara, Gujarat, India
,
Shivani Chaudhary 
2   Department of Surgery, Baroda Medical College and SSG Hospital, Vadodara, Gujarat, India
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Abstract

Though posttraumatic cerebrospinal fluid (CSF) rhinorrhea and otorrhea are fairly common, blepharocele and blepharoencephalocele are rare, with only 15 cases reported to date.

A 29-year-old female patient presented with a complaint of swelling of the right eyelid that had begun three months before. The patient had sustained a head injury 24 years prior to presentation.

Imaging studies revealed the presence of a craniopalpebral CSF fistula. The patient underwent successful surgical repair of the fistula with craniotomy and duroplasty by autologous fascia lata graft.

Delayed development of blepharocele 24 years after trauma is unusual, and, to our knowledge, the case herein reported is the first one in the literature.

Resumo

Embora a rinorreia e a otorreia pós-traumática do líquido cefalorraquidiano (LCR) sejam bastante comuns, a blefarocele e a blefaroencefalocele são raras, com apenas 15 casos relatados até o momento.

Paciente do sexo feminino, 29 anos, apresentou queixa de edema em pálpebra direita com início há três meses. O paciente havia sofrido um traumatismo cranioencefálico 24 anos antes da apresentação.

Os exames de imagem revelaram a presença de fístula liquórica craniopalpebral. O paciente foi submetido com sucesso ao reparo cirúrgico da fístula com craniotomia e duroplastia com enxerto autólogo de fáscia lata.

O atraso no desenvolvimento de blefarocele 24 anos após o trauma é incomum e, até onde sabemos, o caso aqui relatado é o primeiro na literatura.

Keywords

blepharocele - craniopalpebral fistula - orbital encephalocele - blepharoencephalocele

Palavras-chave

blefarocele - fístula craniopalpebral - encefalocele orbital - blefaroencefalocele


Publication History

Received: 06 March 2023

Accepted: 21 June 2023

Article published online:
30 October 2023

© 2023. Sociedade Brasileira de Neurocirurgia. This is an open access article published by Thieme under the terms of the Creative Commons Attribution-NonDerivative-NonCommercial License, permitting copying and reproduction so long as the original work is given appropriate credit. Contents may not be used for commercial purposes, or adapted, remixed, transformed or built upon. (https://creativecommons.org/licenses/by-nc-nd/4.0/)

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