Abstract
Inflammatory myofibroblastic tumour is a rare entity in children with few reported series. The extrahepatic bile duct is an unusual location for this tumour. The authors report here the case of an 8-year-old girl presenting with obstructive jaundice due to inflammatory myofibroblastic tumour of the extrahepatic bile ducts with differential diagnosis of obstructive jaundice in children.
Résumé
Une tumeur inflammatoire myofibroblastique est rare chez les enfants. Peu de cas sont rapportés dans la littérature. Les voies biliaires extrahépatiques constituent la localisation préférentielle. Nous décrivons le cas d'une fillette de huit ans présentant un ictère par obstruction en raison d'une tumeur inflammatoire myofibroblastique au niveau des voies biliaires extrahépatiques et discutons des diagnostics différentiels de l'ictère par obstruction chez les enfants.
Resumen
El tumor miofibroblástico inflamatorio es una entidad rara en niños de la que se han publicado pocos casos. Las vías biliares extrahepáticas son una localización muy rara del tumor. Los autores presentan el caso de una niña de 8 años que sufrió ictericia obstructiva debida a un tumor miofibroblástico inflamatorio de las vías biliares extrahepáticas y discuten el diagnóstico diferencial de la ictericia obstructiva en niños.
Zusammenfassung
Ein entzündlicher myofibroblastischer Tumor ist im Kindesalter sehr selten und ungewöhnlich. Noch ungewöhnlicher ist der Ausgangspunkt im Bereich der extrahepatischen Gallenwege. In der vorliegenden Arbeit wird ein 8-jähriges Mädchen vorgestellt, das mit einer obstruktiven Gelbsucht aufgrund eines inflammatorischen myofibroblastischen Tumors der ableitenden Gallenwege erkrankte. Die Differenzialdiagnose und Therapie werden diskutiert.
Key words
Inflammatory pseudotumour - extrahepatic bile duct - inflammatory myofibroblastic tumour - obstructive jaundice
Mots-clés
Pseudotumeur inflammatoire - voies biliaires extrahépatiques - tumeur inflammatoire myofibroblastique - ictère par obstruction
Palabras clave
Tumor miofibroblástico inflamatorio - pseudotumor inflamatorio - vías biliares extrahepáticas - ictericia obstructiva
Schlüsselwörter
Entzündlicher Pseudotumor - extrahepatische Gallenwege - entzündlicher myofibroblastischer Tumor im Kindesalter
References
-
1
Chen H P, Lee S S, Berardi R S.
Inflammatory pseudotumor of the lung: ultrastructural and light microscopic study of a myxomatous variant.
Cancer.
1984;
54
861-865
-
2
Ciftci A O, Çağlar M, Tanyel F C, Balkancı F, Büyükpamukçu N.
Diagnostic aids in inflammatory pseudotumor of the liver.
Pediatr Surg Int.
1995;
10
161-164
-
3
Ciftci A O, Karnak İ, Şenocak M E, Tanyel F C, Büyükpamukçu N.
Surgical injury to the biliary tract in children.
Eur J Pediatr Surg.
2001;
10
100-105
-
4
Coffin C M, Watterson J, Priest J R, Dehner L P.
Extrapulmonary inflammatory myofibroblastic tumor (inflammatory pseudotumor).
Am J Surg Pathol.
1995;
19
859-872
-
5
Freud E, Bilik R, Yaniv I. et al .
Inflammatory pseudotumor in childhood. A diagnostic and therapeutic dilemma.
Arch Surg.
1991;
126
653-655
-
6
Haith E E, Kepes J J, Holder T M.
Inflammatory pseudotumor involving the common bile duct of a six-year-old boy: Successful pancreatico-duodenectomy.
Surgery.
1964;
56
436-441
-
7
Heneghan M A, Kaplan C G, Priebe Jr C J, Partin J S.
Inflammatory pseudotumor of the liver: A rare cause of obstructive jaundice and portal hypertension in a child.
Pediatr Radiol.
1984;
14
433-435
-
8
Hertzer N R, Hawk W A, Hermann R E.
Inflammatory lesions of the liver which simulate tumor: report of two cases in children.
Surgery.
1971;
69
839-846
-
9
Ikeda H, Oka T, Imafuku I. et al .
A case of inflammatory pseudotumor of the gallbladder and bile duct.
Am J Gastroenterol.
1990;
85
203-206
-
10
Karnak İ, Şenocak M E, Ciftci A O. et al .
Inflammatory myofibroblastic tumor in children: Diagnosis and treatment.
J Pediatr Surg.
2001;
36
908-912
-
11
Kutluk T, Emir S, Karnak İ, Çağlar M.
Mesenteric inflammatory pseudotumor: An unusual presentation with leukemoid reaction and massive calcified mass.
J Pediatr Hematol Oncol.
2001;
24
158-159
-
12
McClain M B, Burton E M, Day D S.
Pancreatic pseudotumor in an 11-year-old child: Imaging findings.
Pediatr Radiol.
2000;
30
610-613
-
13
Meis J M, Enzinger F M.
Inflammatory fibrosarcoma of the mesentery and retroperitoneum: A tumor closely simulating inflammatory pseudotumor.
Am J Surg Pathol.
1991;
15
1146-1156
-
14
Ötgün İ, Karnak İ, Haliloğlu M, Şenocak M E.
Obstructive jaundice due to primary choledochal hydatid cyst mimicking radiologically choledochal cyst.
J Pediatr Surg.
2003;
38
256-258
-
15
Pettinato G, Manivel J C, De Rosa N, Dehner L P.
Inflammatory myofibroblastic tumor (plasma cell granuloma).
Am J Pathol.
1990;
94
538-546
-
16
Pokorny C S, Painter D M, Waugh R C. et al .
Inflammatory pseudotumor of the liver causing biliary obstruction: Treatment by biliary stenting with 5 year follow-up.
J Clin Gastroenterol.
1991;
13
338-341
-
17
Souid A K, Ziemba M C, Dubansky A S. et al .
Inflammatory myofibroblastic tumor in children.
Cancer.
1993;
72
2042-2048
-
18
Stamatakis J D, Howard E R, Williams R.
Benign inflammatory tumor of the common bile duct.
Br J Surg.
1979;
66
257-258
-
19
Vujanic G M, Dojcinov D.
Inflammatory pseudotumor of the lung in children.
Pediatr Hematol Oncol.
1991;
8
121-129
Associate Professor of Paediatric Surgery, M.D. İbrahim Karnak
Hacettepe University Faculty of Medicine
Yenişehir
06100 Ankara
Turkey
eMail: ikarnak@hacettepe.edu.tr
