Abstract
Inflammatory myofibroblastic tumour is a rare entity in children with few reported
series. The extrahepatic bile duct is an unusual location for this tumour. The authors
report here the case of an 8-year-old girl presenting with obstructive jaundice due
to inflammatory myofibroblastic tumour of the extrahepatic bile ducts with differential
diagnosis of obstructive jaundice in children.
Résumé
Une tumeur inflammatoire myofibroblastique est rare chez les enfants. Peu de cas sont
rapportés dans la littérature. Les voies biliaires extrahépatiques constituent la
localisation préférentielle. Nous décrivons le cas d'une fillette de huit ans présentant
un ictère par obstruction en raison d'une tumeur inflammatoire myofibroblastique au
niveau des voies biliaires extrahépatiques et discutons des diagnostics différentiels
de l'ictère par obstruction chez les enfants.
Resumen
El tumor miofibroblástico inflamatorio es una entidad rara en niños de la que se han
publicado pocos casos. Las vías biliares extrahepáticas son una localización muy rara
del tumor. Los autores presentan el caso de una niña de 8 años que sufrió ictericia
obstructiva debida a un tumor miofibroblástico inflamatorio de las vías biliares extrahepáticas
y discuten el diagnóstico diferencial de la ictericia obstructiva en niños.
Zusammenfassung
Ein entzündlicher myofibroblastischer Tumor ist im Kindesalter sehr selten und ungewöhnlich.
Noch ungewöhnlicher ist der Ausgangspunkt im Bereich der extrahepatischen Gallenwege.
In der vorliegenden Arbeit wird ein 8-jähriges Mädchen vorgestellt, das mit einer
obstruktiven Gelbsucht aufgrund eines inflammatorischen myofibroblastischen Tumors
der ableitenden Gallenwege erkrankte. Die Differenzialdiagnose und Therapie werden
diskutiert.
Key words
Inflammatory pseudotumour - extrahepatic bile duct - inflammatory myofibroblastic
tumour - obstructive jaundice
Mots-clés
Pseudotumeur inflammatoire - voies biliaires extrahépatiques - tumeur inflammatoire
myofibroblastique - ictère par obstruction
Palabras clave
Tumor miofibroblástico inflamatorio - pseudotumor inflamatorio - vías biliares extrahepáticas
- ictericia obstructiva
Schlüsselwörter
Entzündlicher Pseudotumor - extrahepatische Gallenwege - entzündlicher myofibroblastischer
Tumor im Kindesalter
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Associate Professor of Paediatric Surgery, M.D. İbrahim Karnak
Hacettepe University Faculty of Medicine
Yenişehir
06100 Ankara
Turkey
Email: ikarnak@hacettepe.edu.tr
