Patient with Positional Wheezing due to Endobronchial Lipomatous Hamartoma

Abstract

Endobronchial hamartoma is a rare form of pulmonary hamartoma, and endobronchial lipomatous hamartomas are even rarer. We describe the case of a 39-year-old man who presented with a two-year history of dyspnea on exertion and wheezing over the left chest only while lying on his left side. The patient was diagnosed with endobronchial lipomatous hamartoma occluding the left main bronchus. He underwent a superior segmentectomy of the left lower lobe, which promptly relieved the dyspnea and positional wheezing. To our knowledge, fewer than 10 such cases are cited in the English literature, none of which presented with positional wheezing. This patient represents the first case of focal and positional wheezing resulting from endobronchial lipomatous hamartoma.

Key words

Airway (including related subject matter) - bronchial disease (including injury, stenosis, tumor, etc.) - lung - benign or congenital lesions

References

• 1 Ko J M, Jung J I, Park S H et al. Benign tumors of the tracheobronchial tree: CT-pathologic correlation.  Am J Roentgenol. 2006;  186 1304-1313
• 2 Wilson R W, Kirejczyk W. Pathological and radiological correlation of endobronchial neoplasms: Part I, benign tumors.  Ann Diagn Pathol. 1997;  1 31-46
• 3 Yilmaz S, Ekici A, Erdogan S, Ekici M. Endobronchial lipomatous hamartoma: CT and MR imaging features.  Eur Radiol. 2004;  14 1521-1524
• 4 Gjevre J A, Myers J L, Prakash U B. Pulmonary hamartomas.  Mayo Clin Proc. 1996;  71 14-20
• 5 Walls J T, Scrivner D L, Jagpal R, Curtis J J. Endobronchial hamartoma.  South Med J. 1984;  77 757-759
• 6 Eppinga P, van der Laan K T, Overbeek J J, Meinesz A F, Postmus P E. Benign endobronchial tumours treated by neodymium-YAG laser.  Eur Respir J. 1988;  1 568-570
• 7 Ortiz-Saracho J, Picher J, Garcia-Rull S, Reboiras S D, Perez I. Endobronchial hamartoma resected by rigid bronchoscope.  Eur J Cardiothorac Surg. 1993;  7 445-446
• 8 Salminen U S. Pulmonary hamartoma. A clinical study of 77 cases in a 21-year period and review of literature.  Eur J Cardiothorac Surg. 1990;  4 15-18